Test–retest reliability for performance-based outcome measures among individuals with arthrogryposis multiplex congenita

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Author(s)Sions, Jaclyn Megan
Author(s)Donohoe, Maureen
Author(s)Beisheim-Ryan, Emma Haldane
Author(s)Pohlig, Ryan Todd
Author(s)Shank, Tracy Michele
Author(s)Nichols, Louise Reid
Date Accessioned2022-06-06T19:58:40Z
Date Available2022-06-06T19:58:40Z
Publication Date2022-02-05
DescriptionThis article was originally published in BMC Musculoskeletal Disorders. The version of record is available at: https://doi.org/10.1186/s12891-022-05070-wen_US
AbstractBackground: Most individuals with arthrogryposis multiplex congenita, a rare condition characterized by joint contractures in ≥ 2 body regions, have foot and ankle involvement leading to compromised gait and balance. The purpose of this study was to establish between-days, test–retest reliability for performance-based outcome measures evaluating gait and balance, i.e., the 10-m Walk Test, Figure-of-8 Walk Test, 360-degree Turn Test, and modified Four Square Step Test, among adolescents and adults with arthrogryposis multiplex congenita. Methods: This reliability study included ambulatory participants, aged 10 to 50 years, with a medical diagnosis of arthrogryposis multiplex congenita. Participants completed performance-based measures, in a randomized order, on two separate occasions. Intraclass correlation coefficients with 95% confidence intervals and minimal detectable changes at the 90% and 95% confidence level were calculated. Results: Participants included 38 community-ambulators with a median of 13 out of 14 upper and lower joint regions affected. Intraclass correlation coefficient point estimates and 95% confidence intervals ranged from .85-.97 and .70-.98, respectively. Minimal detectable changes were 10 to 39% of sample means and were largest for the modified Four Square Step Test. Conclusions: Among individuals with arthrogryposis, gait speed per the 10-m Walk Test, as well as non-linear walking and dynamic balance assessment per the Figure-of-8 Walk and 360 Degree Turn Tests, have adequate test–retest reliability enabling evaluation of individual patient changes. Changes in groups of ambulatory individuals with arthrogryposis multiplex congenita may be reliably evaluated with all of the studied outcome measures.en_US
SponsorThis research was supported, in part, by Run with Jack, the Eunice Kennedy Shriver National Institute of Child Health and Human Development of the National Institutes of Health [grant number: T32HD007490], and Promotion of Doctoral Studies I and II scholarships from the Foundation for Physical Therapy Research awarded to EHB. The content is solely the responsibility of the authors and does not necessarily represent the official views of the funding sources.en_US
CitationSions, J.M., Donohoe, M., Beisheim-Ryan, E.H. et al. Test–retest reliability for performance-based outcome measures among individuals with arthrogryposis multiplex congenita. BMC Musculoskelet Disord 23, 121 (2022). https://doi.org/10.1186/s12891-022-05070-wen_US
ISSN1471-2474
URLhttps://udspace.udel.edu/handle/19716/30963
Languageen_USen_US
PublisherBMC Musculoskeletal Disordersen_US
KeywordsArthrogryposisen_US
KeywordsClubfooten_US
KeywordsGaiten_US
KeywordsPostural balanceen_US
KeywordsWalking speeden_US
TitleTest–retest reliability for performance-based outcome measures among individuals with arthrogryposis multiplex congenitaen_US
TypeArticleen_US
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